OMIA:002272-9796 : Thrombasthenia, atypical, SEL1L-related in Equus caballus (domestic horse)

Categories: Haematopoietic system phene

Links to possible relevant human trait(s) and/or gene(s) in OMIM: 602329 (gene)

Single-gene trait/disorder: yes

Mode of inheritance: Autosomal recessive

Disease-related: yes

Key variant known: yes

Year key variant first reported: 2025

Cross-species summary: Renamed from Thrombasthenia, atypical [17/07/2025]

Species-specific name: Atypical Equine Thrombasthenia

Species-specific symbol: AET

Molecular basis: Dahlgren et al. (2025): "A missense variant in SEL1L (c.1810A>G38 p.Ile604Val) was found in AET [Atypical Equine Thrombasthenia]-affected horses, which [the authors] show is associated with decreased protein expression. SEL1L is intracellular in equine platelets and localizes to the surface upon activation with thrombin. Platelets from homozygous horses exhibit significant decreases in spreading on immobilized collagen."

Clinical features: Dahlgren et al. (2025): "AET results in reduced platelet response to the physiological agonist thrombin, leading to abnormal bleeding after vascular injury [Fry et al., 2005; Norris et al. 2006]. Furthermore, this inhibition can result in prolonged bleeding and, in one reported case, epistaxis during racing [Fry et al., 2005]."

Breed: Thoroughbred (Horse) (VBO_0001083).
Breeds in which the phene or likely causal variants have been documented. If a likely causal variant has been documented, see variant-specific breed information in the variant table. (Breed information may be incomplete).

Associated gene:

Symbol Description Species Chr Location OMIA gene details page Other Links
SEL1L SEL1L adaptor subunit of ERAD E3 ubiquitin ligase Equus caballus 24 NC_091707.1 (39093301..39042698) SEL1L Ensembl, NCBI gene

Variants

By default, variants are sorted chronologically by year of publication, to provide a historical perspective. Readers can re-sort on any column by clicking on the column header. Click it again to sort in a descending order. To create a multiple-field sort, hold down Shift while clicking on the second, third etc relevant column headers.

WARNING! Inclusion of a variant in this table does not automatically mean that it should be used for DNA testing. Anyone contemplating the use of any of these variants for DNA testing should examine critically the relevant evidence (especially in breeds other than the breed in which the variant was first described). If it is decided to proceed, the location and orientation of the variant sequence should be checked very carefully.

Since October 2021, OMIA includes a semiautomated lift-over pipeline to facilitate updates of genomic positions to a recent reference genome position. These changes to genomic positions are not always reflected in the ‘acknowledgements’ or ‘verbal description’ fields in this table.

OMIA Variant ID Breed(s) Variant Phenotype Gene Allele Variant Type Variant Effect Source of Genetic Variant Pathogenicity Classification* Reference Sequence Chr. g. or m. c. or n. p. Verbal Description EVA ID Year Published PubMed ID(s) Acknowledgements
1819 Thoroughbred (Horse) Thrombasthenia, atypical SEL1L substitution missense Naturally occurring variant Not currently evaluated EquCab3.0 24 NC_009167.3:g.26081856T>C NM_001317264.1:c.1810A>G NP_001304193.1:p.Ile604Val 2025 40654876

* Variant pathogenicity for single gene diseases as evaluated by an expert panel of the International Society of Animal Genetics (ISAG) Animal Genetic Testing Standardization Standing Committee

Contact us

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Cite this entry

Nicholas, F. W., Tammen, I., & Sydney Informatics Hub. (2025). OMIA:002272-9796: Online Mendelian Inheritance in Animals (OMIA) [dataset]. https://omia.org/. https://doi.org/10.25910/2AMR-PV70

References

Note: the references are listed in reverse chronological order (from the most recent year to the earliest year), and alphabetically by first author within a year.

2025 Dahlgren, A.R., Careddu, F., Norris, J.W., Adili, R., Kropp, E.M., Li, Q., Holinstat, M., Biunno, I., Balduini, A., Tablin, F., Shavit, J.A., Finno, C.J. :
Identification of the role of SEL1L in platelet function through a multi-species genetic investigation. bioRxiv , 2025. Pubmed reference: 40654876. DOI: 10.1101/2025.04.30.651507.
2021 Dahlgren, A.R., Tablin, F., Finno, C.J. :
Genetics of equine bleeding disorders. Equine Vet J 53:30-37, 2021. Pubmed reference: 32463964. DOI: 10.1111/evj.13290.
2015 Norris, J.W., Pombo, M., Shirley, E., Blevins, G., Tablin, F. :
Association of factor V secretion with protein kinase B signaling in platelets from horses with atypical equine thrombasthenia. J Vet Intern Med 29:1387-94, 2015. Pubmed reference: 26290457. DOI: 10.1111/jvim.13595.
2007 Norris, J.W., Pratt, S.M., Hunter, J.F., Gardner, I.A., Tablin, F. :
Prevalence of reduced fibrinogen binding to platelets in a population of Thoroughbreds. Am J Vet Res 68:716-21, 2007. Pubmed reference: 17605606. DOI: 10.2460/ajvr.68.7.716.
2006 Norris, J.W., Pratt, S.M., Auh, J.H., Wilson, S.J., Clutter, D., Magdesian, K.G., Ferraro, G.L., Tablin, F. :
Investigation of a novel, heritable bleeding diathesis of Thoroughbred horses and development of a screening assay. J Vet Intern Med 20:1450-6, 2006. Pubmed reference: 17186864. DOI: 10.1892/0891-6640(2006)20[1450:ioanhb]2.0.co;2.
2005 Fry, M.M., Walker, N.J., Blevins, G.M., Magdesian, K.G., Tablin, F. :
Platelet function defect in a thoroughbred filly. J Vet Intern Med 19:359-62, 2005. Pubmed reference: 15954553. DOI: 10.1892/0891-6640(2005)19[359:pfdiat]2.0.co;2.

Edit History


  • Created by Frank Nicholas on 02 Jun 2020
  • Changed by Imke Tammen2 on 16 Jun 2024
  • Changed by Imke Tammen2 on 17 Jul 2025